Histoplasmosis is a systemic mycosis caused by the histoplasma capsulatum, primarily affects lungs where it is generally asymptomatic. Histoplasma capsulatum is a saprophyte fungus found in contaminated soils with chicken feathers and droppings. The histoplasmosis affecting jaws is a rare presentation. The objective of this paper is to present a case of this pathology with unfrequent presentation, as well as the treatment protocol used. It is described a patient with histoplasmosis who was referred to the Buco Maxilofacial service of the Domingo Luciani Hospital.

Case report: 58-Year-old female patient from Agua blanca, Edo. Portuguesa (rural area) occupation agriculture. The patient is hypertensive, ambulation on her own, with no movement limitation. She presented facial deformity, swelling in medium and superior third, reactive injury on left paranasal region. Intraoral exam revealed osseous expansion of maxillary with purulent exudative. The patient initiated the current illness approximately a year ago the process. Culture of hard palate and ethmoides was made in which histoplasma was observed. To this date the patient is under observation by a multidisciplinary team.

Conclusion: This report underlines the clinical, radiographic and histopathological characteristics to perform an early diagnostic and shows the severity of the disease in this atypical presentation.

Conflict of interest : None declared.